Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Baylor Genetics | RCV001335842 | SCV001529084 | uncertain significance | Adams-Oliver syndrome 5 | 2018-07-13 | criteria provided, single submitter | clinical testing | This variant was determined to be of uncertain significance according to ACMG Guidelines, 2015 [PMID:25741868]. |
Gene |
RCV005054361 | SCV005688542 | uncertain significance | not provided | 2024-08-01 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Has not been previously published as pathogenic or benign to our knowledge |
Daryl Scott Lab, |
RCV005256775 | SCV005911503 | uncertain significance | NOTCH1-related disorder | 2024-04-01 | criteria provided, single submitter | clinical testing | PM2, PP3 |
Ambry Genetics | RCV005372653 | SCV006039543 | uncertain significance | Familial thoracic aortic aneurysm and aortic dissection | 2025-02-15 | criteria provided, single submitter | clinical testing | The p.Y550D variant (also known as c.1648T>G), located in coding exon 10 of the NOTCH1 gene, results from a T to G substitution at nucleotide position 1648. The tyrosine at codon 550 is replaced by aspartic acid, an amino acid with highly dissimilar properties. This amino acid position is conserved. In addition, this alteration is predicted to be deleterious by in silico analysis. Based on the available evidence, the clinical significance of this variant remains unclear. |