Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000704495 | SCV000833446 | benign | Adams-Oliver syndrome 5 | 2024-10-08 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV000766057 | SCV000897513 | uncertain significance | Aortic valve disease 1; Adams-Oliver syndrome 5 | 2018-10-31 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV000704495 | SCV002553390 | uncertain significance | Adams-Oliver syndrome 5 | 2022-03-15 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV002270978 | SCV002553391 | uncertain significance | Aortic valve disease 1 | 2022-03-15 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004649288 | SCV005142124 | uncertain significance | Familial thoracic aortic aneurysm and aortic dissection | 2024-05-08 | criteria provided, single submitter | clinical testing | The p.V1599M variant (also known as c.4795G>A), located in coding exon 26 of the NOTCH1 gene, results from a G to A substitution at nucleotide position 4795. The valine at codon 1599 is replaced by methionine, an amino acid with highly similar properties. This amino acid position is poorly conserved in available vertebrate species. In addition, this alteration is predicted to be tolerated by in silico analysis. Based on the available evidence, the clinical significance of this variant remains unclear. |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV004768592 | SCV005381400 | uncertain significance | not specified | 2024-08-05 | criteria provided, single submitter | clinical testing | Variant summary: NOTCH1 c.4795G>A (p.Val1599Met) results in a conservative amino acid change located in the Notch, NOD domain (IPR010660) of the encoded protein sequence. Four of five in-silico tools predict a damaging effect of the variant on protein function. The variant allele was found at a frequency of 2.1e-05 in 1584424 control chromosomes in the gnomAD database, including 1 homozygote. This frequency is not significantly higher than estimated for a pathogenic variant in NOTCH1 causing Aortic Valve Disease (2.1e-05 vs 3.1e-05), allowing no conclusion about variant significance (though it does exceed the expected frequency for an Adams-Oliver disease associated variant). To our knowledge, no occurrence of c.4795G>A in individuals affected with NOTCH1-related conditions and no experimental evidence demonstrating its impact on protein function have been reported. ClinVar contains an entry for this variant (Variation ID: 580837). Based on the evidence outlined above, the variant was classified as uncertain significance. |