Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Lupski Lab, |
RCV000234877 | SCV000291987 | pathogenic | Primary ciliary dyskinesia 23 | 2013-04-03 | criteria provided, single submitter | research | This compound heterzygous mutation was predicted to be loss-of-function. |
Labcorp Genetics |
RCV000234877 | SCV005835228 | pathogenic | Primary ciliary dyskinesia 23 | 2024-06-02 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Glu672*) in the ARMC4 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in ARMC4 are known to be pathogenic (PMID: 23849778). This variant is present in population databases (rs771920114, gnomAD 0.0009%). This premature translational stop signal has been observed in individual(s) with clinical features of primary ciliary dyskinesia (PMID: 23849778). ClinVar contains an entry for this variant (Variation ID: 242860). For these reasons, this variant has been classified as Pathogenic. |