Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001986323 | SCV002287213 | uncertain significance | not provided | 2021-09-21 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. This variant has not been reported in the literature in individuals affected with UNC45A-related conditions. This variant is present in population databases (rs766346918, ExAC 0.001%). This sequence change creates a premature translational stop signal (p.Ala256Glyfs*11) in the UNC45A gene. It is expected to result in an absent or disrupted protein product. However, the current clinical and genetic evidence is not sufficient to establish whether loss-of-function variants in UNC45A cause disease. |
Institute of Human Genetics, |
RCV003883735 | SCV004698046 | pathogenic | Cholestasis-edema syndrome, Norwegian type | 2024-02-01 | criteria provided, single submitter | clinical testing | Criteria applied: PVS1,PM2_SUP,PM3_SUP |