Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001977123 | SCV002251820 | uncertain significance | 2-aminoadipic 2-oxoadipic aciduria | 2021-07-19 | criteria provided, single submitter | clinical testing | This variant is present in population databases (rs767599280, ExAC 0.009%). This sequence change replaces alanine with threonine at codon 899 of the DHTKD1 protein (p.Ala899Thr). The alanine residue is highly conserved and there is a small physicochemical difference between alanine and threonine. This variant has not been reported in the literature in individuals affected with DHTKD1-related conditions. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. |