Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001955510 | SCV002213763 | uncertain significance | 2-aminoadipic 2-oxoadipic aciduria | 2021-11-28 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Possibly Damaging"; Align-GVGD: "Class C0"). This variant has not been reported in the literature in individuals affected with DHTKD1-related conditions. This variant is present in population databases (rs200814440, gnomAD 0.007%). This sequence change replaces glycine, which is neutral and non-polar, with alanine, which is neutral and non-polar, at codon 322 of the DHTKD1 protein (p.Gly322Ala). |
Ambry Genetics | RCV002562119 | SCV003555583 | uncertain significance | Inborn genetic diseases | 2020-12-19 | criteria provided, single submitter | clinical testing | The c.965G>C (p.G322A) alteration is located in exon 5 (coding exon 5) of the DHTKD1 gene. This alteration results from a G to C substitution at nucleotide position 965, causing the glycine (G) at amino acid position 322 to be replaced by an alanine (A). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |