Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002035157 | SCV002109105 | uncertain significance | not provided | 2022-09-13 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with cysteine, which is neutral and slightly polar, at codon 809 of the ADAMTSL4 protein (p.Arg809Cys). This variant is present in population databases (rs143844555, gnomAD 0.006%). This variant has not been reported in the literature in individuals affected with ADAMTSL4-related conditions. ClinVar contains an entry for this variant (Variation ID: 1349227). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV002545654 | SCV003734754 | uncertain significance | Inborn genetic diseases | 2022-02-03 | criteria provided, single submitter | clinical testing | The c.2425C>T (p.R809C) alteration is located in exon 15 (coding exon 13) of the ADAMTSL4 gene. This alteration results from a C to T substitution at nucleotide position 2425, causing the arginine (R) at amino acid position 809 to be replaced by a cysteine (C). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |
Genome- |
RCV003339762 | SCV004049622 | uncertain significance | Ectopia lentis et pupillae | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003339761 | SCV004049623 | uncertain significance | Ectopia lentis 2, isolated, autosomal recessive | 2023-04-11 | criteria provided, single submitter | clinical testing |