Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001387658 | SCV001588330 | pathogenic | Cone-rod dystrophy 13; Leber congenital amaurosis 6 | 2022-07-26 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Glu455Lysfs*2) in the RPGRIP1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in RPGRIP1 are known to be pathogenic (PMID: 11528500, 23105016). For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 1074385). This premature translational stop signal has been observed in individual(s) with bone spicules, nyctalopia, and vision loss (Invitae). This variant is present in population databases (rs763671264, gnomAD 0.01%). |