Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Pediatrics Genetics, |
RCV004587653 | SCV005073691 | likely pathogenic | Renal tubular acidosis, distal, 3, with or without sensorineural hearing loss | 2024-07-01 | criteria provided, single submitter | clinical testing | A homozygous nonsense variant in exon 15 of the ATP6V0A4 gene (chr7:g.138739581C>A) that results in a stop codon and premature truncation of the protein at codon 511 (p.Gly511Ter; ENST00000310018.7) was detected (Table). The observed variant lies in the "V-type ATPase 116kDa subunit family" domain of the ATP6V0A4 protein (PF01496). The variant has not been reported in the 1000 genomes, gnomAD (v3.1), gnomdAD (v2.1), topmed. The in-silico prediction of the variant is damaging by MutationTaster2. The reference codon is conserved across species. |