Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ce |
RCV000994534 | SCV001148128 | uncertain significance | not provided | 2017-03-01 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000994534 | SCV002243673 | pathogenic | not provided | 2024-10-22 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine, which is neutral and non-polar, with proline, which is neutral and non-polar, at codon 214 of the DEAF1 protein (p.Leu214Pro). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individual(s) with clinical features of autosomal dominant DEAF1-related conditions (PMID: 30923367). In at least one individual the variant was observed to be de novo. ClinVar contains an entry for this variant (Variation ID: 806590). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt DEAF1 protein function with a positive predictive value of 95%. For these reasons, this variant has been classified as Pathogenic. |
Gene |
RCV000994534 | SCV005327983 | pathogenic | not provided | 2024-02-20 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 30923367, 35032046) |