Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Baylor Genetics | RCV000680145 | SCV000807590 | uncertain significance | Microcephalic primordial dwarfism due to ZNF335 deficiency | 2017-09-01 | criteria provided, single submitter | clinical testing | This variant was found once in our laboratory in trans with a frameshift variant (S915fs) in a 3-year-old female with idiopathic pulmonary arterial hypertension, significant delays, hypotonis, microcephaly, dysmorphisms, broad thumbs and halluxes, hirsutism. A similarly affected microcephalic sister was also compound heterozygous. |
Mendelics | RCV000680145 | SCV002519987 | pathogenic | Microcephalic primordial dwarfism due to ZNF335 deficiency | 2022-05-04 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002532188 | SCV002964598 | uncertain significance | not provided | 2022-03-10 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. ClinVar contains an entry for this variant (Variation ID: 561147). This variant has not been reported in the literature in individuals affected with ZNF335-related conditions. The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This variant, c.724_726del, results in the deletion of 1 amino acid(s) of the ZNF335 protein (p.Val242del), but otherwise preserves the integrity of the reading frame. |
Duke University Health System Sequencing Clinic, |
RCV000680145 | SCV003919025 | uncertain significance | Microcephalic primordial dwarfism due to ZNF335 deficiency | 2023-04-20 | criteria provided, single submitter | research |