Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001851663 | SCV002247155 | pathogenic | not provided | 2021-10-09 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This sequence change replaces phenylalanine with serine at codon 1888 of the CDH23 protein (p.Phe1888Ser). The phenylalanine residue is highly conserved and there is a large physicochemical difference between phenylalanine and serine. This variant is not present in population databases (ExAC no frequency). This missense change has been observed in individual(s) with autosomal recessive deafness (PMID: 15829536). It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 4924). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Not Available"; Align-GVGD: "Class C65"). |
OMIM | RCV000005206 | SCV000025383 | pathogenic | Autosomal recessive nonsyndromic hearing loss 12 | 2005-04-14 | no assertion criteria provided | literature only |