Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetics and Prenatal Diagnosis Center, |
RCV001420154 | SCV001622418 | pathogenic | 3-methylcrotonyl-CoA carboxylase 2 deficiency | 2021-05-13 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001420154 | SCV002240362 | pathogenic | 3-methylcrotonyl-CoA carboxylase 2 deficiency | 2023-10-05 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln198*) in the MCCC2 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in MCCC2 are known to be pathogenic (PMID: 11181649, 22642865). This variant is present in population databases (rs764286389, gnomAD 0.01%). This premature translational stop signal has been observed in individual(s) with 3-methylcrotonyl-CoA carboxylase (PMID: 17968484). ClinVar contains an entry for this variant (Variation ID: 1098284). For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV001420154 | SCV004194346 | pathogenic | 3-methylcrotonyl-CoA carboxylase 2 deficiency | 2023-12-17 | criteria provided, single submitter | clinical testing |