Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002514107 | SCV003440846 | pathogenic | Hypogonadotropic hypogonadism 2 with or without anosmia; Pfeiffer syndrome | 2022-08-19 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. Experimental studies have shown that this missense change affects FGFR1 function (PMID: 18596921, 19820032). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). ClinVar contains an entry for this variant (Variation ID: 16303). This missense change has been observed in individual(s) with clinical features of Kallmann syndrome (PMID: 18596921, 20696889, 31748124, 33442024). In at least one individual the variant was observed to be de novo. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces arginine, which is basic and polar, with glutamine, which is neutral and polar, at codon 250 of the FGFR1 protein (p.Arg250Gln). |
Reproductive Endocrine Unit, |
RCV000030940 | SCV003932530 | pathogenic | Hypogonadotropic hypogonadism 2 with or without anosmia | 2023-05-04 | criteria provided, single submitter | research | |
OMIM | RCV000030940 | SCV000037973 | risk factor | Hypogonadotropic hypogonadism 2 with or without anosmia | 2013-05-02 | no assertion criteria provided | literature only |