Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000549641 | SCV000636907 | pathogenic | Hajdu-Cheney syndrome | 2017-05-06 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. While this particular variant has not been reported in the literature, loss-of-function variants in NOTCH2 are known to be pathogenic (PMID: 16773578, 22209762). This sequence change deletes 1 nucleotide from exon 30 of the NOTCH2 mRNA (c.5345delA), causing a frameshift at codon 1782. This creates a premature translational stop signal (p.Asp1782Alafs*38) and is expected to result in an absent or disrupted protein product. |