Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000542146 | SCV000655884 | uncertain significance | Combined oxidative phosphorylation defect type 27 | 2019-07-18 | criteria provided, single submitter | clinical testing | In summary, this variant has uncertain impact on CARS2 function. The available evidence is currently insufficient to determine its role in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). This variant has not been reported in the literature in individuals with a CARS2-related disease. This variant is present in population databases (rs201349963, ExAC 0.01%). This sequence change replaces histidine with tyrosine at codon 294 of the CARS2 protein (p.His294Tyr). The histidine residue is highly conserved and there is a moderate physicochemical difference between histidine and tyrosine. |