Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000523361 | SCV000617430 | pathogenic | not provided | 2022-10-13 | criteria provided, single submitter | clinical testing | Identified in two unrelated individuals from cohorts of patients with Kleefstra syndrome and intellectual disability in the published literature (Willemsen et al., 2012; Grozeva et al., 2015); Frameshift variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); De novo variant with confirmed parentage in a patient referred for genetic testing at GeneDx; however, the reported clinical features are only partially consistent with the features typically observed in individuals with pathogenic variants in this gene; This variant is associated with the following publications: (PMID: 26350204, 22670141) |
Laboratory of Genetics, |
RCV004720270 | SCV005045806 | pathogenic | Kleefstra syndrome 1 | criteria provided, single submitter | curation |