Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001550671 | SCV001771038 | uncertain significance | not provided | 2023-08-02 | criteria provided, single submitter | clinical testing | Has not been previously published as pathogenic or benign to our knowledge; In silico analysis supports that this missense variant does not alter protein structure/function |
Labcorp Genetics |
RCV001550671 | SCV002424599 | benign | not provided | 2023-03-14 | criteria provided, single submitter | clinical testing | |
Genetic Services Laboratory, |
RCV003151339 | SCV003839377 | uncertain significance | not specified | 2022-08-23 | no assertion criteria provided | clinical testing | DNA sequence analysis of the COQ8B gene demonstrated a sequence change, c.706G>A, in exon 8 that results in an amino acid change, p.Val236Met. This sequence change does not appear to have been previously described in individuals with COQ8B-related disorders. This sequence change has been described in the gnomAD database with a frequency of 0.27% in the African subpopulation and 0.024% in the overall population (dbSNP rs146225943). The p.Val236Met change affects a highly conserved amino acid residue located in a domain of the COQ8B protein that is known to be functional. In-silico pathogenicity prediction tools (SIFT, PolyPhen2, Align GVGD, REVEL) provide contradictory results for the p.Val236Met substitution. Due to insufficient evidences and the lack of functional studies, the clinical significance of the p.Val236Met change remains unknown at this time. |
Prevention |
RCV003948584 | SCV004759732 | likely benign | COQ8B-related disorder | 2022-02-23 | no assertion criteria provided | clinical testing | This variant is classified as likely benign based on ACMG/AMP sequence variant interpretation guidelines (Richards et al. 2015 PMID: 25741868, with internal and published modifications). |