Total submissions: 7
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Eurofins Ntd Llc |
RCV000177662 | SCV000229564 | uncertain significance | not provided | 2017-07-25 | criteria provided, single submitter | clinical testing | |
Center for Pediatric Genomic Medicine, |
RCV000177662 | SCV000280622 | uncertain significance | not provided | 2015-06-12 | criteria provided, single submitter | clinical testing | Converted during submission to Uncertain significance. |
Gene |
RCV000177662 | SCV000518769 | likely benign | not provided | 2021-01-07 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001080328 | SCV000634655 | likely benign | Familial aplasia of the vermis; Meckel-Gruber syndrome; Nephronophthisis | 2024-01-31 | criteria provided, single submitter | clinical testing | |
Ce |
RCV000177662 | SCV004700164 | likely benign | not provided | 2023-12-01 | criteria provided, single submitter | clinical testing | CEP290: BS1 |
Natera, |
RCV001273073 | SCV001455660 | likely benign | Leber congenital amaurosis | 2020-04-17 | no assertion criteria provided | clinical testing | |
Genetic Services Laboratory, |
RCV003150971 | SCV003839351 | uncertain significance | not specified | 2022-05-10 | no assertion criteria provided | clinical testing | DNA sequence analysis of the CEP290 gene demonstrated a sequence change, c.4102G>A, in exon 32 that results in an amino acid change, p.Asp1368Asn. This sequence change has been described in the gnomAD database with a frequency of 0.54% in the African/African American subpopulation (dbSNP rs184143186). The p.Asp1368Asn change affects a poorly conserved amino acid residue located in a domain of the CEP290 protein that is not known to be functional. The p.Asp1368Asn substitution appears to be benign using several in-silico pathogenicity prediction tools (SIFT, PolyPhen2, Align GVGD, REVEL). This sequence change does not appear to have been previously described in individuals with CEP290-related disorders. Due to insufficient evidences and the lack of functional studies, the clinical significance of the p.Asp1368Asn change remains unknown at this time. |