Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000413047 | SCV000490882 | likely pathogenic | not provided | 2024-08-21 | criteria provided, single submitter | clinical testing | Considered a low penetrance variant for autosomal dominant and recessive inherited tooth agenesis (PMID: 31433103); this variant has been observed in at least one homozygous individual in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 23167694, 23991204, 24449199, 31589614, 33034246, 36294409, 36250548, 25545742, 31433103, 35999385) |
Labcorp Genetics |
RCV001080960 | SCV001106314 | likely benign | Odonto-onycho-dermal dysplasia; Tooth agenesis, selective, 4 | 2025-01-14 | criteria provided, single submitter | clinical testing | |
MGZ Medical Genetics Center | RCV000991159 | SCV002579111 | likely pathogenic | Tooth agenesis, selective, 4 | 2022-06-13 | criteria provided, single submitter | clinical testing | |
Institute for Clinical Genetics, |
RCV000413047 | SCV004026391 | uncertain significance | not provided | 2023-05-22 | criteria provided, single submitter | clinical testing | PP3 |
Prevention |
RCV004530509 | SCV004120619 | likely pathogenic | WNT10A-related disorder | 2023-05-09 | criteria provided, single submitter | clinical testing | The WNT10A c.337C>T variant is predicted to result in the amino acid substitution p.Arg113Cys. This variant has been reported in the homozygous, compound heterozygous, and heterozygous states in multiple individuals with tooth agenesis (Arte et al. 2013. PubMed ID: 23991204; Mostowska et al. 2014. PubMed ID: 25545742). Functional study showed that this variant decreased WNT signaling, although some activity was retained (Zeng et al. 2020. PubMed ID: 33034246). This variant is reported in 0.66% of alleles in individuals of European (Finnish) descent in gnomAD (http://gnomad.broadinstitute.org/variant/2-219747106-C-T). This variant is interpreted as likely pathogenic. |
Reproductive Health Research and Development, |
RCV000991159 | SCV001142326 | likely pathogenic | Tooth agenesis, selective, 4 | 2020-01-06 | no assertion criteria provided | curation | NM_025216.2:c.337C>T in the WNT10A gene has an allele frequency of 0.007 in European (Finnish) subpopulation in the gnomAD database. This variant has been reported previously in the homozygous, reportedly compound heterozygous, and heterozygous state in multiple individuals with tooth agenesis (PMID: 23991204). Pathogenic computational verdict because pathogenic predictions from DANN, DEOGEN2, EIGEN, FATHMM-MKL, M-CAP, MVP, MutationAssessor, MutationTaster, REVEL and SIFT. Taken together, we interprete this variant as Pathogenic/Likely pathogenic. ACMG/AMP Criteria applied: PP3; PP4; PM3_Strong. |