Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000158044 | SCV000207979 | uncertain significance | RASopathy | 2012-04-02 | criteria provided, single submitter | clinical testing | This variant is denoted c.22delG at the cDNA level or at the protein level as p.Val8CysfsX95. The normal sequence with the base that is deleted in braces is: GCCG{G}TGCT. The c.22delG single nucleotide deletion has not been published as a mutation, nor has it been reported as a benign polymorphism to our knowledge. The c.22delG mutation in the MAP2K2 gene causes a frameshift starting with codon Valine 8, changes this amino acid to a Cysteine residue, and creates a premature Stop codon at position 95 of the new reading frame, denoted p.Val8CysfsX95. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. In MAP2K2, no truncating or other loss-of function mutations have been reported so far in association with a Noonan spectrum disorder. Therefore, the c.22delG variant is considered to be a variant of unknown clinical significance. The variant is found in NOONAN panel(s). |