Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001873729 | SCV002204970 | uncertain significance | RASopathy | 2022-07-23 | criteria provided, single submitter | clinical testing | Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant is not likely to affect RNA splicing. ClinVar contains an entry for this variant (Variation ID: 1174505). This variant has not been reported in the literature in individuals affected with MAP2K2-related conditions. The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This sequence change affects codon 176 of the MAP2K2 mRNA. It is a 'silent' change, meaning that it does not change the encoded amino acid sequence of the MAP2K2 protein. This variant also falls at the last nucleotide of exon 4, which is part of the consensus splice site for this exon. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Fulgent Genetics, |
RCV001528135 | SCV002777434 | uncertain significance | Cardiofaciocutaneous syndrome 4 | 2021-12-30 | criteria provided, single submitter | clinical testing | |
Clinical Genetics Laboratory, |
RCV001528135 | SCV001739343 | likely pathogenic | Cardiofaciocutaneous syndrome 4 | 2021-05-05 | no assertion criteria provided | clinical testing |