Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV004782691 | SCV005395802 | uncertain significance | not specified | 2024-09-17 | criteria provided, single submitter | clinical testing | Variant summary: TUBB1 c.4C>T (p.Arg2Cys) results in a non-conservative amino acid change in the encoded protein sequence. Five of five in-silico tools predict a damaging effect of the variant on protein function. The variant allele was found at a frequency of 8e-06 in 251432 control chromosomes. The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. c.4C>T has been reported in the literature in at-least one individual affected with bleeding disorder (Almazni_2020). These report(s) do not provide unequivocal conclusions about association of the variant with Autosomal Dominant Macrothrombocytopenia TUBB1-Related. To our knowledge, no experimental evidence demonstrating an impact on protein function has been reported. The following publication has been ascertained in the context of this evaluation (PMID: 32935436). ClinVar contains an entry for this variant (Variation ID: 988869). Based on the evidence outlined above, the variant was classified as uncertain significance. |
Birmingham Platelet Group; University of Birmingham | RCV001270589 | SCV001450888 | uncertain significance | Abnormal bleeding; Thrombocytopenia | 2020-05-01 | no assertion criteria provided | research |