Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001932430 | SCV002132902 | uncertain significance | Cerebral cavernous malformation 2 | 2021-05-18 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine with arginine at codon 115 of the CCM2 protein (p.Leu115Arg). The leucine residue is highly conserved and there is a moderate physicochemical difference between leucine and arginine. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Experimental studies have shown that this variant affects CCM2 protein function (PMID: 25525273). This variant has been observed in individual(s) with cerebral cavernous malformation (PMID: 25525273, Invitae). This variant is not present in population databases (ExAC no frequency). |