Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000690574 | SCV000818264 | uncertain significance | Cerebral cavernous malformation 2 | 2018-07-31 | criteria provided, single submitter | clinical testing | This sequence change replaces serine with proline at codon 116 of the CCM2 protein (p.Ser116Pro). The serine residue is highly conserved and there is a moderate physicochemical difference between serine and proline. This variant is not present in population databases (ExAC no frequency). This variant has been observed in a family affected with cerebral cavernous malformations (Invitae). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive, but these predictions have not been confirmed by published functional studies and their clinical significance is uncertain. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
OMIM | RCV000690574 | SCV004023350 | pathogenic | Cerebral cavernous malformation 2 | 2023-08-04 | no assertion criteria provided | literature only |