Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clinical Genomics Laboratory, |
RCV003459004 | SCV004177144 | pathogenic | Developmental and epileptic encephalopathy, 54 | 2023-07-26 | criteria provided, single submitter | clinical testing | The HNRNPU c.2295_2298del (p.Tyr765fs) variant, to our knowledge, has not been reported in the medical literature and is absent from the general population (gnomAD v.2.1.1), indicating it is not a common variant. This variant causes a frameshift by deleting four nucleotides, leading to a premature termination codon, which is predicted to lead to nonsense mediated decay. Additionally, other variants in this region that introduce a premature termination codon have been described in affected individuals and are considered pathogenic (Leduc MS et al., PMID: 28815871; Taylor J et al., PMID: 35138025). Based on available information and the ACMG/AMP guidelines for variant interpretation (Richards S et al., PMID: 25741868), this variant is classified as pathogenic. |