Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002548193 | SCV002303317 | uncertain significance | Developmental and epileptic encephalopathy, 54 | 2021-12-02 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. This variant disrupts a region of the HNRNPU protein in which other variant(s) (p.Tyr824*) have been observed in individuals with HNRNPU-related conditions (PMID: 23708187). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. This variant has not been reported in the literature in individuals affected with HNRNPU-related conditions. This variant is not present in population databases (gnomAD no frequency). This sequence change results in a frameshift in the HNRNPU gene (p.Asn797Lysfs*56). While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 29 amino acid(s) of the HNRNPU protein and extend the protein by 26 additional amino acid residues. |