Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Baylor Genetics | RCV000454263 | SCV001527130 | uncertain significance | Usher syndrome type 2C | 2018-06-22 | criteria provided, single submitter | clinical testing | This variant was determined to be of uncertain significance according to ACMG Guidelines, 2015 [PMID:25741868]. |
King Laboratory, |
RCV000454263 | SCV001976379 | likely pathogenic | Usher syndrome type 2C | 2020-08-01 | criteria provided, single submitter | research | Analysis of patient-derived RNA indicates that ADGRV1 c.10426+1G>A disrupts the donor splice site of ADGRV1 exon 49, leading to transcriptional loss of 209bp and a premature stop (Abu Rayyan 2020). The variant is homozygous in 3 Palestinian children with moderate to severe hearing loss from 3 different families. The variant is absent from 1300 Palestinian controls and absent from public databases. |
Hereditary Research Laboratory, |
RCV000454263 | SCV000538092 | pathogenic | Usher syndrome type 2C | 2016-06-04 | no assertion criteria provided | research | congenital, moderate to severe |