Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003770225 | SCV004654426 | pathogenic | not provided | 2023-02-01 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This premature translational stop signal has been observed in individual(s) with Usher syndrome (PMID: 33089500). This variant is present in population databases (rs780664266, gnomAD 0.003%). This sequence change creates a premature translational stop signal (p.Ser4880*) in the ADGRV1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in ADGRV1 are known to be pathogenic (PMID: 19357117, 22135276, 22147658, 26226137, 30718709, 31047384, 32467589). |
National Institute on Deafness and Communication Disorders, |
RCV001199957 | SCV001370754 | pathogenic | Usher syndrome type 2A | 2019-12-10 | no assertion criteria provided | research |