Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Prevention |
RCV003411691 | SCV004113459 | pathogenic | POLR3GL-related disorder | 2023-08-21 | criteria provided, single submitter | clinical testing | The POLR3GL c.-41-1G>A variant is located in the 5' untranslated region. This variant was reported in the compound heterozygous state along with another variant affecting splicing in an individual with endosteal hyperostosis and oligodontia, with RNA studies demonstrating this variant disrupts splicing (Terhal. 2020. PubMed ID: 31089205). This variant is reported in 0.0048% of alleles in individuals of European (Non-Finnish) descent in gnomAD (http://gnomad.broadinstitute.org/variant/1-145460264-C-T). This variant is interpreted as pathogenic. |
Genome Diagnostics Laboratory, |
RCV000766136 | SCV000882436 | likely pathogenic | Short stature; Abnormal facial shape; Oligodontia; Hyperostosis | 2019-01-23 | no assertion criteria provided | clinical testing | |
OMIM | RCV001328379 | SCV001519500 | pathogenic | Short stature, oligodontia, dysmorphic facies, and motor delay | 2021-03-17 | no assertion criteria provided | literature only |