Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV004018192 | SCV004848726 | likely pathogenic | Citrullinemia type I | 2022-08-26 | criteria provided, single submitter | clinical testing | The c.1128-1delG in ASS1 has been not been previoulsy reported in individuals with citrullinemia and was absent from large population databases. This variant occurs within the canonical splice site (+/- 1,2) and is predicted to cause altered splicing leading to an abnormal or absent protein. Loss of function of the ASS1 gene is an established disease mechanism in autosomal recessive citrullinemia. In summary, although additional studies are required to fully establish its clinical significance, this variant meets criteria to be classified as likely pathogenic for autosomal recessive citrullinemia. ACMG/AMP criteria applied: PVS1, PM2_Supporting. |