Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000002427 | SCV002316531 | likely pathogenic | Ehlers-Danlos syndrome, musculocontractural type | 2024-11-21 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with proline, which is neutral and non-polar, at codon 213 of the CHST14 protein (p.Arg213Pro). This variant is present in population databases (rs121908257, gnomAD 0.05%). This missense change has been observed in individual(s) with clinical features of CHST14-related conditions (PMID: 20004762, 26373698, 34815299). ClinVar contains an entry for this variant (Variation ID: 2337). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt CHST14 protein function with a positive predictive value of 80%. Experimental studies have shown that this missense change affects CHST14 function (PMID: 20004762). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
OMIM | RCV001290021 | SCV000022585 | pathogenic | Ehlers-Danlos syndrome, musculocontractural type 1 | 2009-12-01 | no assertion criteria provided | literature only | |
Uni |
RCV000002427 | SCV000091173 | not provided | Ehlers-Danlos syndrome, musculocontractural type | no assertion provided | not provided |