Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000498640 | SCV000589519 | pathogenic | not provided | 2024-07-29 | criteria provided, single submitter | clinical testing | Intronic variant directly or indirectly altering the +5 splice site in a gene for which loss of function is a known mechanism of disease, and published functional studies demonstrate a damaging effect (PMID: 11440989, 11810270, 36927155); Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 25525159, 14961560, 11440989, 11810270, 20157015, 25641387, 25794858, 20417570, 24907432, 25044830, 34242285, 11440988, 27656661, 28926202, 33841295, Macuada[article]2024, 38219857, 36927155) |
Athena Diagnostics | RCV000498640 | SCV000614391 | likely pathogenic | not provided | 2017-04-28 | criteria provided, single submitter | clinical testing | |
Ce |
RCV000498640 | SCV001246477 | pathogenic | not provided | 2024-06-01 | criteria provided, single submitter | clinical testing | OPA1: PM1, PM2, PM6, PS3:Moderate, PS4:Moderate, PP4 |
3billion, |
RCV000678587 | SCV002318547 | pathogenic | Autosomal dominant optic atrophy classic form | 2022-03-22 | criteria provided, single submitter | clinical testing | The variant has been observed in multiple (>3) similarly affected unrelated individuals (PMID: 11440989, 14961560, 20417570, 25137924) and co-segregated with Optic atrophy 1, in multiple affected family members (PMID: 20417570). The variant has been reported at least twice as pathogenic/likely pathogenic with clinical assertions and evidence for the classification (ClinVar ID: VCV000431939). It is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.000004). Therefore, this variant is classified as pathogenic according to the recommendation of ACMG/AMP guideline. |
Joint Genome Diagnostic Labs from Nijmegen and Maastricht, |
RCV000678587 | SCV000804669 | likely pathogenic | Autosomal dominant optic atrophy classic form | 2016-09-01 | no assertion criteria provided | clinical testing |