Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Athena Diagnostics | RCV001659726 | SCV001880546 | pathogenic | not provided | 2021-01-25 | criteria provided, single submitter | clinical testing | This variant has not been reported in large, multi-ethnic general populations (http://gnomad.broadinstitute.org). This variant appears to segregate with disease in at least one family. Assessment of experimental evidence suggests this variant results in abnormal protein function. This variant reduced the protein's GTP hydrolysis activity (PMID: 20185555, 30293569). |
Labcorp Genetics |
RCV001659726 | SCV002236722 | pathogenic | not provided | 2022-10-19 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) has been performed at Invitae for this missense variant, however the output from this modeling did not meet the statistical confidence thresholds required to predict the impact of this variant on OPA1 protein function. ClinVar contains an entry for this variant (Variation ID: 30461). This missense change has been observed in individual(s) with autosomal dominant OPA1-related conditions (PMID: 18065439, 18158317). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces serine, which is neutral and polar, with arginine, which is basic and polar, at codon 545 of the OPA1 protein (p.Ser545Arg). |
Centre for Inherited Metabolic Diseases, |
RCV002464072 | SCV002605369 | pathogenic | Autosomal dominant optic atrophy classic form | 2022-11-22 | criteria provided, single submitter | clinical testing | |
OMIM | RCV000023415 | SCV000044706 | pathogenic | Optic atrophy with or without deafness, ophthalmoplegia, myopathy, ataxia, and neuropathy | 2010-03-01 | no assertion criteria provided | literature only | |
Wellcome Centre for Mitochondrial Research, |
RCV000508898 | SCV000575922 | pathogenic | Mitochondrial disease | 2017-04-07 | no assertion criteria provided | clinical testing |