Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV000779159 | SCV000915674 | uncertain significance | Congenital dyserythropoietic anemia, type I | 2018-10-18 | criteria provided, single submitter | clinical testing | The CDAN1 c.2539C>T (p.Gln847Ter) variant is a stop-gained variant that is predicted to result in an absent or truncated protein. This variant has been reported in a compound heterozygous state with a missense variant in one individual with congenital dyserythropoietic anemia (Tamary et al. 2005). The p.Gln847Ter variant was absent from 154 controls but is reported at a frequency of 0.001164 in the European American population of the Exome Sequencing Project. However, this frequency is based on one allele only in a region of good sequencing coverage, so the variant is presumed to be rare. Due to the potential impact of stop-gained variants and the supporting evidence, the p.Gln847Ter variant is classified as a variant of unknown significance but suspicious for pathogenicity for congenital dyserythropoietic anemia. This variant was observed by ICSL as part of a predisposition screen in an ostensibly healthy population. |