Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000671958 | SCV000797005 | pathogenic | Autosomal recessive polycystic kidney disease | 2018-01-08 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000671958 | SCV003439395 | pathogenic | Autosomal recessive polycystic kidney disease | 2022-05-22 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 556021). This premature translational stop signal has been observed in individual(s) with polycystic kidney disease (PMID: 27225849). This variant is not present in population databases (gnomAD no frequency). This sequence change creates a premature translational stop signal (p.Gln1473*) in the PKHD1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in PKHD1 are known to be pathogenic (PMID: 19940839). |