Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Research Laboratory of Ophthalmology and Vision Sciences, |
RCV001839052 | SCV001809935 | likely pathogenic | Weill-Marchesani 4 syndrome, recessive | 2021-08-03 | no assertion criteria provided | clinical testing | The c.2984G>A (p.R995Q) variant in ADAMTS17 was identified in a Chinese family with autosomal recessive Weill-Marchesani syndrome, which was compound heterozygous with the c.2254A>G variant and segregated in this family of five individuals. The c.2984G>A variant was reported in dbSNP (rs1289240183) with a frequency of 0.00007 in the European population and 0.00000 in Asia. In addition, the amino acid site is highly conserved in various animals, and the variant was suggested to be damaging in some in silico prediction programs. Thus, we consider this variant as likely pathogenic. |