Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000200702 | SCV000251169 | likely pathogenic | not provided | 2013-06-25 | criteria provided, single submitter | clinical testing | p.Leu262Pro (CTG>CCG): c.785 T>C in exon 8 of the ATPAF2 gene (NM_145691.3). The L262P missense change has not been published as a mutation, nor has it been reported as a benign polymorphism to our knowledge. The amino acid change is semi-conservative as both Leucine and Proline are uncharged, non-polar amino acids, but the introduction of Proline with its unique ring structure may affect the secondary structure of the ATPAF2 protein. This change occurs at a highly conserved position in the ATPAF2 protein, and multiple in-silico analysis programs predict that L262P is damaging to the ATPAF2 protein. Therefore, L262P is a strong candidate for a disease-causing mutation, however the possibility that it is a benign variant cannot be excluded. The variant is found in MITONUC-MITOP panel(s). |
New York Genome Center | RCV001838990 | SCV002099375 | uncertain significance | Mitochondrial complex V (ATP synthase) deficiency, nuclear type 1 | 2021-02-26 | criteria provided, single submitter | clinical testing |