Total submissions: 1
| Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
|---|---|---|---|---|---|---|---|---|
| Clinical Genomics Laboratory, |
RCV005052199 | SCV005685192 | uncertain significance | Intellectual developmental disorder, autosomal recessive 75, with neuropsychiatric features and variant lissencephaly | 2024-09-08 | criteria provided, single submitter | clinical testing | The PIDD1 c.2605G>T (p.Val869Leu) variant, to our knowledge, has not been reported in the medical literature. This variant is only observed on 33/277,858 alleles in the general population (gnomAD v.2.1.1), indicating it is not a common variant. Computational predictors are uncertain as to the impact of this variant on PIDD1 function. This variant resides within a region called the Death Domain, amino acids 788-873, of PIDD1 that is defined as a critical functional domain (Sheikh TI et al., PMID: 33414379). Due to limited information, and based on ACMG/AMP guidelines for variant interpretation (Richards S et al., PMID: 25741868), the clinical significance of this variant is uncertain at this time. |