Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000669317 | SCV000794059 | likely pathogenic | Ellis-van Creveld syndrome | 2017-09-07 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001052473 | SCV001216685 | pathogenic | Ellis-van Creveld syndrome; Curry-Hall syndrome | 2023-09-21 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 553798). This variant has been observed in individual(s) with Ellis-van Creveld syndrome (PMID: 21199751). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. This variant is present in population databases (rs755789146, gnomAD 0.006%). This variant results in the deletion of part of exon 8 (c.871-2_894del) of the EVC2 gene. It is expected to disrupt RNA splicing. Variants that disrupt the donor or acceptor splice site typically lead to a loss of protein function (PMID: 16199547), and loss-of-function variants in EVC2 are known to be pathogenic (PMID: 17024374, 19810119, 19876929). |