Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001849915 | SCV002232575 | pathogenic | Dystonia 12 | 2021-02-16 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine with arginine at codon 947 of the ATP1A3 protein (p.Gly947Arg). The glycine residue is moderately conserved and there is a moderate physicochemical difference between glycine and arginine. This variant is not present in population databases (ExAC no frequency). This missense change has been observed in individual(s) with alternating hemiplegia of childhood (PMID: 22842232). In at least one individual the variant was observed to be de novo. ClinVar contains an entry for this variant (Variation ID: 139579). This variant has been reported to affect ATP1A3 protein function (PMID: 24631656). This variant disrupts the p.Gly947 amino acid residue in ATP1A3. Other variant(s) that disrupt this residue have been determined to be pathogenic (Invitae). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. |
OMIM | RCV000128466 | SCV000172168 | pathogenic | Alternating hemiplegia of childhood 2 | 2014-01-01 | no assertion criteria provided | literature only | |
Gene |
RCV001849915 | SCV000195726 | not provided | Dystonia 12 | no assertion provided | literature only |