Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Revvity Omics, |
RCV003135073 | SCV003809143 | uncertain significance | not provided | 2019-05-08 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV003135073 | SCV004293137 | pathogenic | not provided | 2023-05-29 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 2435127). This premature translational stop signal has been observed in individual(s) with Dowling–Degos disease (PMID: 24387993, 29931677). This variant is present in population databases (rs140695299, gnomAD 0.01%). This sequence change creates a premature translational stop signal (p.Arg132*) in the POGLUT1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in POGLUT1 are known to be pathogenic (PMID: 24387993). |