Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000666116 | SCV000790359 | likely pathogenic | Cohen syndrome | 2017-03-16 | criteria provided, single submitter | clinical testing | |
Invitae | RCV000666116 | SCV002237204 | pathogenic | Cohen syndrome | 2021-05-26 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This variant has not been reported in the literature in individuals with VPS13B-related conditions. ClinVar contains an entry for this variant (Variation ID: 551135). This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Met437*) in the VPS13B gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in VPS13B are known to be pathogenic (PMID: 15141358, 16648375, 20461111). |