Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000634094 | SCV000755372 | benign | Cohen syndrome | 2024-01-30 | criteria provided, single submitter | clinical testing | |
Mayo Clinic Laboratories, |
RCV001356249 | SCV001714883 | uncertain significance | not provided | 2019-10-21 | criteria provided, single submitter | clinical testing | |
Genetic Services Laboratory, |
RCV001821796 | SCV002071434 | uncertain significance | not specified | 2018-06-12 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV003905700 | SCV004719186 | likely benign | VPS13B-related disorder | 2022-06-13 | criteria provided, single submitter | clinical testing | This variant is classified as likely benign based on ACMG/AMP sequence variant interpretation guidelines (Richards et al. 2015 PMID: 25741868, with internal and published modifications). |
Natera, |
RCV000634094 | SCV001460393 | likely benign | Cohen syndrome | 2019-11-11 | no assertion criteria provided | clinical testing | |
Department of Pathology and Laboratory Medicine, |
RCV001356249 | SCV001551364 | uncertain significance | not provided | no assertion criteria provided | clinical testing | The VPS13B p.Val1987Leu variant was not identified in the literature nor was it identified in Cosmic or LOVD 3.0. The variant was identified in dbSNP (ID: rs375399419) and in ClinVar (classified as a VUS by Invitae for Cohen syndrome). The variant was also identified in control databases in 34 of 250242 chromosomes at a frequency of 0.000136 (Genome Aggregation Database Feb 27, 2017). The variant was observed in the following populations: Ashkenazi Jewish in 17 of 10060 chromosomes (freq: 0.00169), Latino in 9 of 34420 chromosomes (freq: 0.000262), Other in 1 of 6094 chromosomes (freq: 0.000164) and European (non-Finnish) in 7 of 113206 chromosomes (freq: 0.000062); it was not observed in the African, East Asian, European (Finnish) and South Asian populations. The variant occurs outside of the splicing consensus sequence and 3 of 4 in silico or computational prediction software programs (SpliceSiteFinder, NNSPLICE, GeneSplicer) do not predict a difference in splicing. The p.Val1987 residue is conserved in mammals but not more distantly related organisms and computational analyses (PolyPhen-2, SIFT, AlignGVGD, BLOSUM, MutationTaster) provide inconsistent predictions regarding the impact to the protein; this information is not very predictive of pathogenicity. In summary, based on the above information the clinical significance of this variant cannot be determined with certainty at this time. This variant is classified as a variant of uncertain significance. |