Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000411201 | SCV000485842 | likely pathogenic | Cohen syndrome | 2016-02-23 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000411201 | SCV004471928 | pathogenic | Cohen syndrome | 2023-11-13 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Ile3028Metfs*15) in the VPS13B gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in VPS13B are known to be pathogenic (PMID: 15141358, 16648375, 20461111). This variant is present in population databases (no rsID available, gnomAD 0.003%). This variant has not been reported in the literature in individuals affected with VPS13B-related conditions. ClinVar contains an entry for this variant (Variation ID: 370501). For these reasons, this variant has been classified as Pathogenic. |