Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000412084 | SCV000485960 | likely pathogenic | Cohen syndrome | 2016-03-07 | criteria provided, single submitter | clinical testing | |
Invitae | RCV000412084 | SCV002196670 | pathogenic | Cohen syndrome | 2023-06-07 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 370602). This variant has not been reported in the literature in individuals affected with VPS13B-related conditions. This variant is present in population databases (rs774357106, gnomAD 0.003%). This sequence change creates a premature translational stop signal (p.Ile3284Phefs*32) in the VPS13B gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in VPS13B are known to be pathogenic (PMID: 15141358, 16648375, 20461111). |