Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001903893 | SCV002174941 | uncertain significance | not provided | 2024-06-12 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with histidine, which is basic and polar, at codon 1298 of the SAMD9L protein (p.Arg1298His). This variant is present in population databases (no rsID available, gnomAD 0.006%). This variant has not been reported in the literature in individuals affected with SAMD9L-related conditions. ClinVar contains an entry for this variant (Variation ID: 1405557). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt SAMD9L protein function with a negative predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Johns Hopkins Genomics, |
RCV002282643 | SCV002570255 | uncertain significance | Ataxia-pancytopenia syndrome | 2022-05-07 | criteria provided, single submitter | clinical testing | This SAMD9L variant (rs1010548594) is rare (<0.1%) in a large population dataset (gnomAD: 2/249554 total alleles; 0.0008%; no homozygotes) and has been reported in ClinVar. This missense variant has not been reported in individuals with SCA49 in the literature. Three bioinformatic tools queried predict that this substitution would be tolerated; the arginine residue at this position is conserved across most primates, but weakly conserved across other vertebrate species assessed. Bioinformatic analysis predicts that this variant would not affect normal exon 5 splicing, although this has not been confirmed experimentally to our knowledge. Due to insufficient evidence, we consider the clinical significance of c.3893G>A to be uncertain at this time. |
Gene |
RCV001903893 | SCV005372045 | uncertain significance | not provided | 2023-07-26 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant does not alter protein structure/function; Has not been previously published as pathogenic or benign to our knowledge; This variant is associated with the following publications: (PMID: 35310830) |
Ambry Genetics | RCV004955793 | SCV005499214 | uncertain significance | Inborn genetic diseases | 2024-12-04 | criteria provided, single submitter | clinical testing | The c.3893G>A (p.R1298H) alteration is located in exon 5 (coding exon 1) of the SAMD9L gene. This alteration results from a G to A substitution at nucleotide position 3893, causing the arginine (R) at amino acid position 1298 to be replaced by a histidine (H). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |