Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV004018205 | SCV004848761 | likely pathogenic | Rare genetic deafness | 2022-08-26 | criteria provided, single submitter | clinical testing | The c.4702-2A>C variant in STRC has not been reported in individuals with disease and was present in 0.01% (9/94622) of chromosomes across all ethnicities by gnomAD (https://gnomad.broadinstitute.org/). This variant occurs within the canonical splice site (+/- 1,2) and is predicted to cause altered splicing leading to an abnormal or absent protein. Loss of function of the STRC gene is an established disease mechanism in autosomal recessive non syndromic hearing loss. In summary, although additional studies are required to fully establish its clinical significance, this variant meets criteria to be classified as likely pathogenic for autosomal recessive non syndromic hearing loss. ACMG/AMP criteria applied: PVS1, PM2_Supporting. |