Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion, |
RCV001808837 | SCV002058988 | likely pathogenic | Bartter disease type 2 | 2022-01-03 | criteria provided, single submitter | clinical testing | A different missense change at the same codon has been reported as pathogenic/likely pathogenic with strong evidence (ClinVar ID: VCV000870374, PM5_M). In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.767, PP3_P). A missense variant is a common mechanism associated with Bartter syndrome (PP2_P). It is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.000044, PM2_M). Therefore, this variant is classified as likely pathogenic according to the recommendation of ACMG/AMP guideline. |