Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001376919 | SCV001574118 | likely pathogenic | Bardet-Biedl syndrome; McKusick-Kaufman syndrome | 2023-07-28 | criteria provided, single submitter | clinical testing | Experimental studies have shown that this missense change affects MKKS function (PMID: 18094050, 20498079, 20502701, 22446187). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt MKKS protein function. ClinVar contains an entry for this variant (Variation ID: 1066030). This missense change has been observed in individual(s) with Bardet-Biedl syndrome (PMID: 12107442). It has also been observed to segregate with disease in related individuals. This variant is present in population databases (rs779116830, gnomAD 0.006%). This sequence change replaces glycine, which is neutral and non-polar, with glutamic acid, which is acidic and polar, at codon 345 of the MKKS protein (p.Gly345Glu). |
SN ONGC Dept of Genetics and Molecular biology Vision Research Foundation | RCV003222313 | SCV003915860 | pathogenic | Bardet-Biedl syndrome | criteria provided, single submitter | research | ||
Baylor Genetics | RCV003473898 | SCV004194883 | likely pathogenic | Bardet-Biedl syndrome 6 | 2023-09-04 | criteria provided, single submitter | clinical testing | |
Genome Diagnostics Laboratory, |
RCV001579882 | SCV001808834 | likely pathogenic | not provided | no assertion criteria provided | clinical testing | ||
Joint Genome Diagnostic Labs from Nijmegen and Maastricht, |
RCV001579882 | SCV001953119 | likely pathogenic | not provided | no assertion criteria provided | clinical testing |